Dural arteriovenous fistula is a rare subtype of intracranial arteriovenous malformation, accounting for 10%-15% of all intracranial vascular malformations, with the characteristic of pathological anastomosis between the dural branch of the dural artery or intracranial artery and dural vein, or meningeal vein, or cortical vein. In this paper, a patient with headache suspected of temporal arteritis was analyzed retrospectively. Ultrasonography showed that arteriovenous fistula supplied by bilateral branches of the superficial temporal artery of the external carotid artery is likely. Finally, a dural arteriovenous fistula was diagnosed using digital subtraction angiography. The case shows that patients with headaches should also pay attention to other rare diseases causing headaches excepted for the temporal arteritis in practice.