Congenital tracheal stenosis complicated with communicating bronchopulmonary foregut malformation in 2 children and literature review
10.3760/cma.j.cn101070-20220704-00820
- VernacularTitle:儿童先天性气管狭窄合并交通性支气管肺前肠畸形2例并文献复习
- Author:
Chao WANG
1
;
Zhiyu FENG
;
Yunpeng ZHAI
;
Yanliang YANG
;
Shaochao WANG
;
Lei WANG
;
Chen MENG
;
Shisong ZHANG
Author Information
1. 山东大学附属儿童医院(济南市儿童医院)呼吸介入科，济南 250022
- Keywords:
Tracheal stenosis, congenital;
Congenital communicating bronchopulmonary foregut malformation;
Child
- From:
Chinese Journal of Applied Clinical Pediatrics
2022;37(24):1907-1910
- CountryChina
- Language:Chinese
-
Abstract:
Objective:To explore the clinical typing, diagnostic method and treatment plan of congenital tracheal stenosis (CTS) combined with communicating bronchopulmonary foregut malformation (CBPFM) in children.Methods:The clinical data of 2 children with CTS and CBPFM who were treated in the Center for Respiratory Intervention of Children′s Hospital Affiliated to Shandong University in May 2021 and January 2022 were retrospectively analyzed.Studies were retrieved from domestic and foreign databases, so as to summarize the clinical characteristics of CTS complicated with CBPFM and investigate the typing method of CBPFM.Results:One patient was a 4-year-old girl, who sought the medical advice due to " recurrent cough and asthma for more than 4 years" . She was diagnosed with typeⅡ CBPFM at the right side and CTS.Surgical thoracoscopic right pneumonectomy plus oesophageal repair was performed.The other patient was a 7-month-and-2-day-old female, who visited the hospital for " difficult eating, dyspnea and purple lip cyanosis for 7 months" . This patient was diagnosed with typeⅡ CBPFM at the left side and CTS.Slide tracheoplasty and left pneumonectomy+ oesophageal repair were performed successively.Eight English and one Chinese studies were collected.Twenty-one children with CBPFM and 12 children with CTS and CBPFM were included.Eleven CTS cases with sufficient diagnostic evidence were complicated with typeⅠA and typeⅡCBPFM.Conclusions:CTS and CBPFM can lead to severe wheezing and dyspnea.Clinicians should enhance their awareness and be more cautious.There may be a potential link between CTS and typeⅠA and typeⅡCBPFM, and further investigation is required.
