Gorham's Disease Involving the Shoulder Joint: A Case Report.
10.4055/jkoa.2002.37.6.810
- Author:
Chul Hong KIM
1
;
Kyu Yeol LEE
;
Min Soo KANG
;
Jin Sook JEONG
Author Information
1. Department of Orthopedic Surgery, College of Medicine, Dong-A University, Busan, Korea. Kimch@daunet.donga.ac.kr
- Publication Type:Case Report
- Keywords:
Shoulder;
Gorham's disease;
Immunopathology;
Radiotherapy;
Antiresorptive medication
- MeSH:
Bone Diseases;
Capillaries;
Female;
Humans;
Osteolysis, Essential;
Radiotherapy;
Shoulder Joint*;
Shoulder*
- From:The Journal of the Korean Orthopaedic Association
2002;37(6):810-813
- CountryRepublic of Korea
- Language:Korean
-
Abstract:
Gorham's disease is a rare vanishing bone disease characterized by massive osteolysis and replacement with numerous wide engorged capillaries. The exact nature and effective treatment modalities for this condition are as yet unclear. A fifty-years old female, who had unexplained destruction of the left shoulder joint, was diagnosed as having Gorham's disease according to histopathological (capillary tissue aggregation) and immunopathological (immunoreactions with IL-1alpha and IL-6) studies. Although we treated her with antiresorptive medication and radiotherapy, which are current treatment modalities, the destructive process progressed. We report upon this case and provide a review of its literature.
