Delayed-onset focal dystonia after diffuse cerebral hypoxia: two case reports.
10.3346/jkms.1993.8.6.476
- Author:
Young Chul CHOI
1
;
Myung Sik LEE
;
Il Saing CHOI
Author Information
1. Department of Neurology, Youngdong Severance Hospital, Yonsei University College of Medicine, Seoul, Korea.
- Publication Type:Case Reports ; Review
- Keywords:
Delayed-onset dystonia;
perinatal anoxia
- MeSH:
Child;
Dystonia/*etiology;
Female;
Humans;
Hypoxia, Brain/*complications;
Male;
Time Factors
- From:Journal of Korean Medical Science
1993;8(6):476-481
- CountryRepublic of Korea
- Language:English
-
Abstract:
The delayed-onset focal dystonia is a rare sequela of cerebrovascular disease or diffuse cerebral hypoxic damage. The responsible lesion sites for the dystonia are variable and the pathogenesis is uncertain. We describe two children with delayed-onset focal dystonia as a complication of perinatal anoxia. The intervals between hypoxic insult and onset of dystonia were 6 years in one and 3 in the other cases. Our patients did not have a focal lesion; one had scattered white matter lesion and the other had a diffuse frontoparietal atrophy. Delayed-onset dystonia after perinatal anoxia can be also caused by non-focal lesion such as diffuse frontoparietal atrophy or cerebral white matter lesion with long interval delay.
