Amniotic constriction band: a report of two cases with unique clinical presentations.
10.5125/jkaoms.2017.43.3.171
- Author:
Sunil RICHARDSON
1
;
Rakshit Vijay KHANDEPARKER
;
Philippe PELLERIN
Author Information
1. Richardsons Dental and Craniofacial Hospital, Nagercoil, India. sunilrichardson145@gmail.com
- Publication Type:Case Report
- Keywords:
Amniotic constriction band;
Circumferential band;
Bilateral cleft lip and palate;
Auto-amputation;
Microphthalmos
- MeSH:
Cicatrix;
Cleft Lip;
Constriction*;
Humans;
Microphthalmos;
Palate;
Thumb
- From:Journal of the Korean Association of Oral and Maxillofacial Surgeons
2017;43(3):171-177
- CountryRepublic of Korea
- Language:English
-
Abstract:
Amniotic constriction band is a rare clinical entity with varied manifestations that range from a combination of congenital malformations to isolated malformations that are unique to each patient. The etiology of this entity remains unknown. Herein, we highlight two cases of amniotic constriction band that presented to our unit with unique clinical characteristics. To the best of our knowledge, an isolated circumferential band of scarring on the face with ocular involvement, as demonstrated by the first case, and a combination of bilateral complete cleft lip and palate with bilateral microphthalmia, auto-amputation of the right thumb, and a constriction band on the left thumb, as demonstrated by the second case, are extremely rare presentations of amniotic constriction band that were not previously reported in the literature and therefore necessitate a special mention. We discuss potential etiologies for these cases and review the existing literature on this entity.
